Abstract
In about 90% of cases, lymphangioma develops within 2 years of age; it rarely occurs in adults. Conventionally, the cases in adults have often been resected surgically. However, postsurgical functional and/or esthetic complications are major hurdles. Here, we report a case of cystic lymphangioma in the submandibular space, which developed in a 31-year-old woman. She presented with an elastic soft, painless mass in the left submandibular region. Imaging findings revealed a multilocular cystic lesion. 15 ml of serous yellow fluid including lymphocytes was aspirated. Consequently, cystic lymphangioma in the left submandibular region was diagnosed. Local injection of OK-432 was performed. The lesion was significantly reduced, and no recurrence was observed at 18 months after initial treatment.